Prevalence of Muscular Dystrophies: A Systematic Literature Review

aut.relation.endpage268
aut.relation.issue3-4en_NZ
aut.relation.journalNeuroepidemiologyen_NZ
aut.relation.startpage259
aut.relation.volume43en_NZ
aut.researcherKrishnamurthi, Rita
dc.contributor.authorTheadom, Aen_NZ
dc.contributor.authorRodrigues, Men_NZ
dc.contributor.authorRoxburgh, Ren_NZ
dc.contributor.authorBalalla, Sen_NZ
dc.contributor.authorHiggins, Cen_NZ
dc.contributor.authorBhattacharjee, Ren_NZ
dc.contributor.authorJones, Ken_NZ
dc.contributor.authorKrishnamurthi, Ren_NZ
dc.contributor.authorFeigin, Ven_NZ
dc.date.accessioned2020-03-15T23:26:46Z
dc.date.available2020-03-15T23:26:46Z
dc.date.copyright2014en_NZ
dc.date.issued2014en_NZ
dc.description.abstractBackground: Determining the prevalence of neuromuscular disorders for the general population is important to identify the scope of burden on society and enable comparisons with other health conditions. This systematic review aims to identify and collate the findings of studies published between 1960 and 2013 on the prevalence of all types of muscular dystrophies. Summary: Relevant articles were identified through electronic database searches and manual searches of reference lists. There were 38 articles from across 19 countries that met the inclusion criteria. The total combined prevalence for all muscular dystrophies for studies classified as having a low risk of bias ranged between 19.8 and 25.1 per 100,000 person-years. Myotonic dystrophy (0.5-18.1 per 100,000), Duchenne muscular dystrophy (1.7-4.2) and facioscapulohumeral muscular dystrophy (3.2-4.6 per 100,000) were found to be the most common types of disorder. There was wide variation in study methodology, case ascertainment, and verification procedures and populations studied, all of which may contribute to the wide prevalence range, in addition to the likely variation in prevalence by country. Key Messages: Greater consistency in the conduct and reporting of neuroepidemiological studies is urgently needed to enable comparisons to be made between studies, countries, and over time.
dc.identifier.citationNeuroepidemiology, 43(3-4), 259-268.
dc.identifier.citationThis is the peer-reviewed but unedited manuscript version of the following article: [see Source]. The final, published version is available at https://www.karger.com/Article/FullText/369343.
dc.identifier.doi10.1159/000369343en_NZ
dc.identifier.urihttps://hdl.handle.net/10292/13206
dc.publisherKarger
dc.relation.urihttps://www.karger.com/Article/FullText/369343
dc.rightsThis is the peer-reviewed but unedited manuscript version of the following article: [see Source]. The final, published version is available at https://www.karger.com/Article/FullText/369343.
dc.rights.accessrightsOpenAccessen_NZ
dc.subjectMuscular dystrophy; Myotonic dystrophy; Epidemiology; Prevalence; Systematic review
dc.titlePrevalence of Muscular Dystrophies: A Systematic Literature Reviewen_NZ
dc.typeJournal Article
pubs.elements-id177166
pubs.organisational-data/AUT
pubs.organisational-data/AUT/Health & Environmental Science
pubs.organisational-data/AUT/Health & Environmental Science/Health Faculty Office
pubs.organisational-data/AUT/Health & Environmental Science/Public Health & Psych Studies
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